improved sensitivity of an acid sphingomyelinase activity assay using a c6:0 sphingomyelin substrate

Clicks: 182
ID: 201832
2015
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Ranked #46 of 57 articles by views in advances in skin & wound care

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Abstract
Short-chain C6-sphingomyelin is an artificial substrate that was used in an acid sphingomyelinase activity assay for a pilot screening study of patients with Niemann–Pick disease types A and B. Using previously published multiplex and single assay conditions, normal acid sphingomyelinase activity levels (i.e. false negative results) were observed in two sisters with Niemann–Pick B who were compound heterozygotes for two missense mutations, p.C92W and p.P184L, in the SMPD1 gene. Increasing the sodium taurocholate detergent concentration in the assay buffer lowered the activity levels of these two patients into the range observed with other patients with clear separation from normal controls.
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chuang2015molecularimproved Use this key to autocite in the manuscript while using SciMatic Manuscript Manager or Thesis Manager
Authors ;Wei-Lien Chuang;Joshua Pacheco;Samantha Cooper;Jonathan S. Kingsbury;John Hinds;Pavlina Wolf;Petra Oliva;Joan Keutzer;Gerald F. Cox;Kate Zhang
Journal advances in skin & wound care
Year 2015
DOI
10.1016/j.ymgmr.2015.04.001
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